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Marfan Syndrome and Pregnancy

Risk

C.H.D.

stands for



CONGENITAL HEART DISEASE

MOTHERS CHD- % OFFSPRING CHD



ONLY CONCERNED with

STRUCTURAL DISORDERS



NOT Congenital ARRYTHMIAS

NOT Congenital Myocardial disorder



Myocardial disorder often with CHD in

syndromes

MOTHERS CHD- % OFFSPRING CHD





WHAT is REAL INCIDENCE overall



?

3-9 %

PROBLEMS and VARIABLES

MOTHERS CHD- % OFFSPRING CHD





VARIABLES

Time/Methods/Who detection



VARIABLES

In MOTHER

MOTHERS CHD- % OFFSPRING CHD



VARIABLES Time

•  FETAL SCAN

•  OFFSPRING post natal

•  PEDIATRIC CARD + FETAL ECHO

•  LONGIT. STUDIES – 10 yrs

RETROSPECTIVE or PROSPECTIVE

ALL MAKE DIFFERENT INCIDENCE

MOTHERS CHD- % OFFSPRING CHD



VARIABLES Time/Methods/Who

•  General scan

•  Specific fetal echo

•  Machinery

•  Experience

OUTCOMES DIFFER

MOTHERS CHD- % OFFSPRING CHD



VARIABLES Time



FETAL SCAN misses mild lesion

As can infant echos.

Lack of info on hearts of abortions



MAKE INCIDENCE CHD

MOTHERS CHD- % OFFSPRING CHD





VARIABLES In MOTHER

•  in PREGNANCY

•  HERSELF

Both affect outcomes

MOTHERS CHD- % OFFSPRING CHD



90-95%

will not have

CONGENITAL HEART DISEASE



CHD HAVE INCREASED x4 -?8 GENETIC POOL



Effects of this is:

Neutralised by fetal scanning ABORTION

DECREASE

MOTHERS CHD- % OFFSPRING CHD

VARIABLES MOTHER - HERSELF

•  FATHER

•  OTHER FAMILY CHD

•  SYNDROMES MOTHER OR FAMILY

•  CONSANGUINITY

•  DRUGS, ALCOHOL, THERAPY

•  DISEASES

•  CHD

•  EFFECTS of CHD [low output, cyanosis]

•  AGE

MOTHERS CHD- % OFFSPRING CHD

VARIABLES MOTHER -

FATHER

OTHER family affected

Consanguinity

SYNDROMES MOTHER OR FAMILY

DRUGS, ALCOHOL, THERAPY

DISEASES

AGE

EFFECTS of CHD [low output, cyanosis]

MOTHERS CHD- % OFFSPRING CHD

VARIABLES MOTHER -

FATHER her choice? Is he ?



•  AGE does not influence

•  Lower incidence affected CHD cf mothers

•  BEWARE if SYNDROMIC

Pregnancy + Congenital Heart Desease

Incidence of CHD in Offspring

TOTAL MOTHER FATHER

4,10 % 5.00 % 2.00 %

Fallot 2.50 % 1.50 %

LV obstruction 10 - 18% 3.00 %

VSD 6.00 % 2.00 %

ASD 4.50 % 1.50 %

MOTHERS CHD- % OFFSPRING CHD

VARIABLES MOTHER

• OTHER FAMILY MEMBERS

CONSANGUINITY

• Considerable increase in incidence if 1 or more

Lesions NOTalways concordant -

CONSANGUNITY increases incidence







Pitkin et al.1990 Ann. Int. Med

• Nora 1988 Amer J Med Genetics

• Nora 1987 Amer J Cardiol

MOTHERS CHD- % OFFSPRING CHD

VARIABLES MOTHER-SYNDROMES



INCREASES

TURNERS

DOWNS

All FUNNY FACES

CHROMOSOME ABNORMALITIES USUAL

MOSTLY SIMPLE CHD ANOMALIES

MOTHERS CHD- % OFFSPRING CHD

VARIABLES MOTHER - HERSELF

•  FATHER

•  OTHER FAMILY CHD

•  SYNDROMES MOTHER OR FAMILY

•  CONSANGUINITY

•  DRUGS, ALCOHOL, THERAPY

•  DISEASES

MOTHERS CHD- % OFFSPRING CHD

VARIABLES MOTHER Diseases, drugs,



INCREASES

Diabetes, Epilepsy, Thyroid,

specific INFECTIONS (CMV, Rubella, HIV)

Lithium, ?/ anti epileptics

ALCOHOL

MOTHERS CHD- % OFFSPRING CHD

VARIABLES MOTHER

•  FATHER

•  OTHER FAMILY CHD

•  SYNDROMES MOTHER OR FAMILY

•  CONSANGUINITY

•  DRUGS, ALCOHOL, THERAPY

•  DISEASES

•  CHD-LESION

• EFFECTS of CHD [low output, cyanosis]

•  AGE

MOTHERS CHD- % OFFSPRING CHD

VARIABLES MOTHERCHD - LESION%

ASD 2

Fallot 3

CCtga 3.6

AV def. 8

VSD 3

AVst. 4

Coarct 3.6

TGA 1

Cyan. 4 Dreuthen et al. 2007 JACC

96 PREGNANCIES



41 (43%) 55 (57,3%)

SURVIVORS SPONT ABORTION





26 (27%) 15 (15,6%)

PREMATURE

AT TERM 1 CHD 1 CHD

2% but ? CHD in spont abortions could be 5 %

Pregnancy and Cyanotic Congenital

Heart Desease

MOTHERS CHD- % OFFSPRING CHD

LEFT HEART ANOMALIES

CAN BE

HERITABLE

Includes Hypoplastic Left Heart

syndrome,

bicuspid aortic valve (BAV)

HLHS in offspring of mothers with BAV



? Offspring of mothers with HLH

CONCLUSIONS

MOTHERS CHD- % OFFSPRING CHD

•  MANY VARIABLES AFFECT INCIDENCE

•  VARIES WITH LESION IN MOTHER



•  OVERALL INCIDENCE 3-8 %

•  EXPERT FETAL ECHO FOR “AT RISK”

MOTHER WITH CHD



VITAL

AT RISK MOTHERS CHD

OFFSPRING CHD



WRONG TO ADVISE CONTINUE

PREGNANCY

IF SEVERE, COMPLEX CVS

MALFORMATION

May ONLY HAVE 1 CHANCE

Define

MOTHERS CHD- % OFFSPRING CHD







??

PRECONCEPTION COUNSELLING

Could REDUCE

C.H.D. in OFFSPRING

MOTHERS CHD- % OFFSPRING CHD









C.H.D. in OFFSPRING

GENETIC & ENVIRONMENTAL

MULTIFACTORIAL!

Nora - 1968

MOTHERS CHD- % OFFSPRING CHD





??

CHOICE OF FATHER

Could REDUCE

C.H.D. in OFFSPRING

What is in the

geans ?

ADIOS VALENCIA



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